Adenoid cystic carcinoma of trachea: A rare tumor managed by diode laser and tracheal resection

Abstract

International Journal of Case Reports and Images (IJCRI) is an international, peer reviewed, monthly, open access, online journal, publishing high-quality, articles in all areas of basic medical sciences and clinical specialties.Aim of IJCRI is to encourage the publication of new information by providing a platform for reporting of unique, unusual and rare cases which enhance understanding of disease process, its diagnosis, management and clinico-pathologic correlations.IJCRI publishes Review Articles, Case Series, Case Reports, Case in Images, Clinical Images and Letters to Editor. Website: www.ijcasereportsandimages.comAdenoid cystic carcinoma of trachea: A rare tumor managed by diode laser and tracheal resection Navin Bhambhani, Jayesh Gori, Vishwanath Masurkar, Sonal Thombre ABSTRACT Introduction: Adenoid cystic carcinoma (ACC) is a rare type of cancer, which mostly occurs in the salivary glands of the head and neck, and has also been reported in other parts including trachea as case reports or small case series. The patient may present as asthma or acute tracheobronchial obstruction and may require urgent management to relive obstruction. It has a propensity to spread along both submucosal and perineural planes which are responsible for late local recurrence even after complete resection. The best results can be obtained by resection with or without adjuvant radiotherapy. Case Report: We report a rare case of endoluminal adenoid cystic carcinoma of the distal trachea presenting with acute tracheal obstruction managed bronchoscopically with high power diode laser followed by segmental resection of trachea and radiotherapy with 18 months of follow-up with no evidence of recurrence. Conclusion:There are only very few reports available for the use of diode laser with flexible bronchoscope in tracheobronchial adenoid cystic carcinoma. However, rarity of such tumors makes it impossible to obtain such data. This technique, in such rare tumors, is safe with almost no or limited morbidity from our experience and available data.

Adenoid cystic carcinoma in trachea: A rare presentation

“…1,2 They mostly have indolent behavior with a prolonged slow and insidious progression, in several years, despite its chances of local recurrences and distant metastasis. 2 However when it is associated with distant metastasis, survival is frequently less than 2 years. 3,6 Metastasis to brain, liver, kidney, skin, abdomen and heart have been reported.…”

“…Adenoid cystic carcinoma is a rare tumor of salivary gland origin, found mostly in head and neck region but has also been reported in breast, lacrimal gland of eye, lung, bartholin's gland, trachea and parasanal sinuses. 1,2 Primary tracheal tumors are rare and constitute only two 2% of all respiratory tract tumors. 1 Adenoid cystic carcinoma is the second most common malignant tracheal tumor after squamous cell carcinoma.…”

“…1 Adenoid cystic carcinoma is the second most common malignant tracheal tumor after squamous cell carcinoma. 1,2 These tumors should be considered because they often present as dyspnea or respiratory distress and hence misdiagnosed and treated as asthma for months to years or sometimes until even with metastasis. 3 We report a case of young male presenting with polypoidal tracheal mass with complains of dyspnea and respiratory distress as initial clinical presentation.…”