We report the case of a 38-year old male patient with sinusitis caused by an infected follicular cyst due to an ectopic impacted third molar in the right maxillary sinus.A 10-day antibiotherapy regimen was administered; subsequently, the cyst and the third molar were removed achieving complete recovery.Fibrous dysplasia was diagnosed at follow-up examination (occupation of the maxillary sinus by bone tissue was observed in a radiographic examination) and confirmed by biopsy.In cases of odontogenic sinusitis, thorough examination is crucial, as evidenced by the case reported in this study.A Literature review was performed in order to identify the diagnostic methods currently available and the clinical features, complications and treatment for both, odontogenic maxillary sinusitis and fibrous dysplasia.