Unilateral Morbihan syndrome

Macca, Laura; Pomi, Federica Li; Motolese, Alfonso; Broganelli, Paolo; Borgia, Francesco

doi:10.4081/dr.2021.9270

Cited by 6 publications

(6 citation statements)

References 5 publications

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“…Morbihan syndrome is so uncommon that it is only reported in case studies [6,[11][12][13]. No previous case reports link the syndrome to TN or show improvement in symptoms following treatment of TN with SRS.…”

Section: Discussionmentioning

confidence: 99%

Treatment of Trigeminal Neuralgia With Stereotactic Radiosurgery Improved Symptoms of Morbihan Syndrome

Burgess¹,

Mula‐Hussain²,

Malone³

2021

Cureus

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Trigeminal neuralgia (TN) is a neuropathic pain disorder characterized by paroxysmal pain in the maxillary and mandibular regions of the face. Morbihan syndrome is a disease that classically presents with dermatologic findings, including progressive facial edema and erythema. There are no previous reports of the onset of trigeminal neuralgia with Morbihan syndrome or previous reports describing improvement in symptoms of Morbihan syndrome with treatment of trigeminal neuralgia. We describe the case of a 62-yearold female who presented with trigeminal neuralgia and shortly thereafter developed significant facial edema and was diagnosed with Morbihan syndrome. The neuralgia was refractory to medical management and was effectively treated with stereotactic radiosurgery (SRS). This coincided with an improvement in her Morbihan syndrome that is now controlled following stereotactic radiosurgery and continued lymphatic massage.

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Section: Discussionmentioning

confidence: 99%

Treatment of Trigeminal Neuralgia With Stereotactic Radiosurgery Improved Symptoms of Morbihan Syndrome

Burgess¹,

Mula‐Hussain²,

Malone³

2021

Cureus

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“…However, this problem has not been the subject of publications so far. 10,11 Our patient, though almost the youngest among those being described, presented with all typical symptoms. Usually, the diagnosis of MS is made after the exclusion of other potential causes of swelling.…”

Section: Discussionmentioning

confidence: 63%

“…1,2,3,10 The skin lesions are usually symmetrical and exceptionally unilateral. 11,12 Pathophysiology is believed to be related to rosacea or acne vulgaris, as one of them is present in most cases of MS before the onset of the swelling. 9,13 Disease usually has a slow and chronic course and doesn't disappear without treatment.…”

Section: Introductionmentioning

confidence: 99%

Omalizumab in the treatment of Morbihan syndrome in an adolescent girl – case report and literature review

Mazurek-Durlak,

Mularczyk,

Kwinta

et al. 2023

Allergol Immunopathol

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Morbihan syndrome (MS) is characterized by solid facial edema, usually related to rosacea or acne vulgaris. The facial edema deforms the patient’s features, can impair peripheral vision, and affects quality of life. Its pathophysiology remains unclear. The disease usually has a slow and chronic course. MS most commonly affects middle-aged Caucasian men with rosacea and is rare in people below 20 years of age. MS is a diagnosis of exclusion. There is no standard treatment for MS, though systemic isotretinoin and antihistamines are mainly used. We present the case of an adolescent girl with MS nonresponding to 19 months of isotretinoin treatment with add-on antihistamines. Therapy with monthly administration of omalizumab (anti-IgE) for 6 months was an effective therapeutic option, improving the quality of life. Our case is the second description of omalizumab use in Morbihan syndrome, the first in an adolescent.

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“…One case report of unilateral Morbihan syndrome reports development of facial symptoms after use of CPAP and history of sleeping on the affected side. 3 More data would be needed to determine whether there is an association with sleeping position and/or CPAP use in the development of Morbihan syndrome.…”

Section: Discussionmentioning

confidence: 99%

Chronic Lymphedema of the Eyelid and Face: Answer

Dougher,

Hurley,

Kalb

et al. 2024

The American Journal of Dermatopathology

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Unilateral Morbihan syndrome

Cited by 6 publications

References 5 publications

Treatment of Trigeminal Neuralgia With Stereotactic Radiosurgery Improved Symptoms of Morbihan Syndrome

Treatment of Trigeminal Neuralgia With Stereotactic Radiosurgery Improved Symptoms of Morbihan Syndrome

Omalizumab in the treatment of Morbihan syndrome in an adolescent girl – case report and literature review

Chronic Lymphedema of the Eyelid and Face: Answer

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