Abstract:Dissecting aneurysm of the intracranial arteries is uncommon and isolated dissection of middle cerebral artery (MCA) is much rarer. Cerebral infarction is the usual presentation of MCA dissection in first two decades, hemorrhagic manifestation being much rare. We describe a young male patient who presented with acute onset headache and left sided hemiparesis due to acute intra-parenchymal hemorrhage. Digital subtraction angiography finally revealed dissection involving M2 segment of right MCA as the possible cause of intracerebral hemorrhage in this patient. This type of uncommon presentation of MCA dissection is rarely reported before.