Aim: To report a case of bilateral anterior and posterior Lenticonus without sensorineural hearing loss,
without renal associations. Case report We describe a case of bilateral anterior and posterior Lenticonus
and absence of family history. No renal association could be identied on urine routine microscopy and ultrasonography of the
abdomen. Clear lens extraction with phacoemulsication with posterior chamber Intraocular lens (PCIOL) was performed for
the patient. Conclusion The presence of bilateral anterior and posterior Lenticonus is rare but may be a presentation of Alport
syndrome. Clear lens extraction with Intraocular lens is a viable treatment option with good visual prognosis.