Primary lingual dystonia induced by speaking

Abstract

We describe a 46-year-old woman who presented with lingual dystonia induced only by speaking, which responded well to anticholinergic treatment.

Botulinum Toxin in the Treatment of Lingual Dystonia Induced by Speaking

“…The pathophysiologic mechanism of primary lingual dystonia induced by speaking remains unclear, and often the treatment of these patients is difficult. Some authors have suggested that anticholinergic medication, such as trihexyphenidyl, may be the treatment of choice in cases with lingual dystonia [1 2 3, 6]. In contrast to these cases, we observed that primary lingual dystonia may be intractable to anticholinergic treatment.…”

“…One important feature of cases with lingual dystonia is responsiveness to sensory tricks [1, 2, 4, 5], for example, how chewing gum effectively relieved symptoms in our patient. However, this sensory trick only lasted for a few weeks, after which she experienced a gradual return of her symptoms.…”

“…The literature includes 6 cases (7 including our patient) of primary lingual dystonia induced by speaking [1 2 3 4 5 6]. …”

“…Primary lingual dystonia is a rare condition, especially when it is only induced by speaking [1 2 3 4 5 6]. There are a few papers in the literature reporting on experience with botulinum toxin for lingual dystonia [7 8 9 10 11].…”

Dystonia of the Oromandibular, Lingual and Laryngeal Areas

“…27 The technique is an intraoral injection performed by following the ramus of the mandible to locate the lateral ptyergoid and injecting approximately 45 units on each side. 28 For jaw closing dystonia, BoNT is injected into the masseter muscle. Palpation of the muscle at the angle of the mandible is performed and 20 units of BoNT are injected into each site.…”