Orthokeratinized odontogenic cyst of the maxilla: report of a case and review of the literature

Abstract

The orthokeratinized odontogenic cyst is a relatively rare developmental odontogenic cyst of the jaws that occurs predominantly in males between the third and fourth decades. According to the 2005 World Health Organization's classification, orthokeratinized odontogenic cyst is not a part of the keratocystic odontogenic tumor spectrum. We present a case of a 41-year-old male with a history of remarkable lingual expansion in the anterior part of the maxilla since last year with rapid growth in the last three months as a unilocular well-defined radiolucent lesion extending from maxillary left central incisor to the right second premolar. Orthokeratinized odontogenic cyst is a specific type of keratinized odontogenic cysts which is completely different from keratocystic odontogenic tumor from the viewpoint of the clinical and pathological features.

Orthokeratinized odontogenic cyst: Report of eight cases and review of literature regarding its malignant transformation

“…OOCs are usually asymptomatic and the most frequent symptom is a slow-growing swelling, which is occasionally associated with pain. [ 12 ] In our study, one patient complained of pain and seven patients had swelling. OOC is a cystic lesion.…”

“…Moreover, MacDonald and Li[ 7 ] reported a preponderance for females in the second decade of life. The most common areas of involvement are the posterior mandible and the mandibular ramus region[ 8 9 12 ] but in our patients, maxilla and mandible were equally involved. OOCs are usually asymptomatic and the most frequent symptom is a slow-growing swelling, which is occasionally associated with pain.…”

Histopathological Examination and Literature Review of Orthokeratinized Odontogenic Cyst

“…Case reports of OCC are shown in Table 1 [4]- [11]. Ten cases were single, and Sex female female femake female male male female male male male Location Lower Molars -ramus 1 0 1 1 1 2 1 1 Many reports described unilocular lesions, although Wright [12], MacDonald et al [16] [17] and Dong et al [18] reported multilocular cases.…”

A Rare Case of Front Mandible Orthokeratinized Odontogenic Cyst – Surgical Management with Preventive Rigid Osteosynthesis

“…These cysts are often asymptomatic and discovered as an incidental finding especially in the orthodontics' radiographs. 4 The OOC is mostly localized in lateral segments of the mandible and extremely rare in the front part of that bone. [4][5][6] To the best knowledge of authors, this is the first case in the literature describing OOC in front mandible.…”

“…4 The OOC is mostly localized in lateral segments of the mandible and extremely rare in the front part of that bone. [4][5][6] To the best knowledge of authors, this is the first case in the literature describing OOC in front mandible. Fractures caused by the underlying pathologic lesion in the mandible, are rare and don't reach 2% of all fractures of the mandible.…”