Odontogenic myxomas are rarely occurring, slow-growing, asymptomatic, and locally aggressive odontogenic tumors with high rate of recurrence, mainly of ectomesenchymal origin. Three-dimensional imaging techniques can be used to diagnose such pathological lesions, but have limited use as they are not cost-effective and are selectively available for better outcome. Following is a case report of OM of a 5-year-old child with a brief discussion on its diagnosis and management.How to cite this articleMukherjee CG, Mukherjee U, Bansal A, Jha A. A Misdiagnosed Odontogenic Tumor: A Clinical Dilemma. Int J Clin Pediatr Dent 2017;10(2):205-207.