Objective: To screen the psychomotor development at 24 months of age in children in whom a positional head deformity (PHD), plagiocephaly or brachycephaly, was detected at birth or in the first months of life. Methods: This retrospective study included children with a PHD detected during a specialist consultation in a tertiary centre. In clinical practice, the standardized Ages and Stages Questionnaire at 24 months (ASQ-24) was filled in by the parents at home and sent back to the hospital. The questionnaire results and the children's perinatal characteristics were studied to determine whether PHD influenced their psychomotor development and identify confounding factors that could affect psychomotor development. Results: Based on the ASQ-24 scores, psychomotor development in at least two ASQ domains was delayed in 13 of the 158 included children (8.23%), a rate not different from what found in the general population at 24 months (5-8%). Among the perinatal characteristics, only intra-uterine growth restriction was associated significantly with psychomotor delay. Conclusion: PHD presence does not associate at the risk of psychomotor delay at 24 months according to the ASQ24 test used in the general population of the same age.