Linear atrophoderma of moulin over face: An exceedingly rare entity

Darung, Ivoreen; Rudra, Olympia; Samanta, Ayan; Agarwal, Megha; Ghosh, Alakendu

doi:10.4103/ijd.ijd_469_16

Cited by 5 publications

(3 citation statements)

References 6 publications

(8 reference statements)

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“…Despite an extensive review of medical literature, the author could find only two cases of LAM localized to the face alone (Table 1). Darung et al (5) have reported a case of a 16-year-old girl having asymptomatic hyperpigmented depressed plaques over the left chin of six months' duration. Similarly, Ozkur et al (12) have described two cases of LAM from Turkey having facial lesions.…”

Section: Discussionmentioning

confidence: 99%

“…Isolated facial involvement in LAM is an exceedingly rare presentation (5). The author could find only two cases of LAM, where the lesions are restricted to the face (5). In this article, the author is presenting the third case of LAM exclusive to face.…”

Section: Introductionmentioning

confidence: 92%

“…Face and neck involvement has rarely been reported in the literature (3,4). Isolated facial involvement in LAM is an exceedingly rare presentation (5). The author could find only two cases of LAM, where the lesions are restricted to the face (5).…”

Section: Introductionmentioning

confidence: 95%

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Linear Atrophoderma of Moulin Localized to Face: An Exceedingly Rare Entity

Arif¹

2020

J Skin Stem Cell

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Introduction: Linear atrophoderma of Moulin (LAM) is a rare dermatologic disorder characterized by hyperpigmented atrophic plaques following the Blaschko lines (BL). The trunk and limbs are the usual sites affected. Isolated facial involvement is an exceedingly rare entity. Despite a comprehensive medical literature search, the author could find only two cases of LAM where the lesions are exclusively localized to the face. In this article, the author presents the third case of LAM localized to face only. Case Presentation: A 26-year-old male complained of multiple linear non-pruritic pigmented lesions over the left side of the nose and glabellar area of six months’ duration. There was no history of erythema, thickening/hardening of skin, or violaceous border surrounding the lesions. On clinical examination, there were multiple hyperpigmented brownish lesions, the majority of which were depressed, involving the left ala and bridge of nose laterally and glabellar area in a Blaschkoid pattern. Diagnosis of LAM was established based on suggestive history and clinical examination. Conclusions: LAM is a rare disorder, and the facial localization makes it exceedingly rare. It should be kept in the differential diagnosis when hyperpigmented depressed lesions are present in a Blaschkoid pattern on the face.

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Section: Discussionmentioning

confidence: 99%

Section: Introductionmentioning

confidence: 92%

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Linear Atrophoderma of Moulin Localized to Face: An Exceedingly Rare Entity

Arif¹

2020

J Skin Stem Cell

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Linear atrophoderma of Moulin: A rare case report and review of the literature

Hussein Al‐janabi,

Diab,

Aljammal

et al. 2024

Skin Health and Disease

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Linear atrophoderma of Moulin (LAM) is an uncommon dermatological disease characterised by linear, depressed plaques typically following Blaschko's lines. LAM generally occurs in adolescence or early adulthood and is more commonly observed in females. The aetiology of LAM is still unclear. We report a rare case of LAM in an 18‐year‐old female presenting with an atypical Blaschkoid distribution (multiple band‐like pattern) on her right trunk. A clinical examination and histopathological analysis were performed to make the diagnosis. Partial improvement was obtained with calcipotriol and colchicine. LAM is a rare condition; we were only able to identify 23 case reports in the published literature. The findings of this report contribute to the limited literature on LAM, highlighting the clinical variability of LAM and suggesting potential novel variants beyond the classic presentation, emphasising the importance of recognising diverse manifestations for accurate diagnosis and management. Early recognition of LAM is crucial for appropriate treatment and improved patient outcomes. Further research is needed to elucidate LAM's aetiology and underlying mechanisms to facilitate the development of more targeted therapeutic strategies.

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