Late Presentation of Anal Canal Duplication in Adults: A Series of Four Rare Cases

Mirzaei, Ramazan; Mahjubi, Bahar; Alvandipoor, Mina; Karami, Mohammad Reza

doi:10.3393/ac.2015.31.1.34

Cited by 41 publications

(21 citation statements)

References 7 publications

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“…In two-thirds of patients, diagnosis is made during the first year of life. In the English-language medical literature, there are no more than nine documented cases of patients older than 15 years of age, who were diagnosed with ACD 2,5,8,9) . Mild symptoms, such as diarrhea, constipation, anal pain, or mucous discharge, occur in 33% of patients, and more severe symptoms, such as recurrent fistulas, skin abscess, or sepsis, occur in 20% of patients.…”

Section: Discussionmentioning

confidence: 99%

“…Anal canal duplication (ACD) is a rare congenital malformation, with only 66 cases reported in the English-language literature since 1970 [1][2][3][4][5][6] . ACD is defined as second anal orifice, located posterior to the true anus.…”

Section: Introductionmentioning

confidence: 99%

“…Other diseases, such as fistula-in-ano or anorectal abscess, need to be differentiated from ACD using anatomical or pathological examination. ACDs are usually detected early in life 2,3) , and only a few cases remain undiagnosed until adulthood 5,8) . Here, we report a rare case of an adult female with ACD, review the clinical and diagnostic features, and discuss the current standard treatment for this condition.…”

Section: Introductionmentioning

confidence: 99%

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Anal Canal Duplication Associated with Presacral Cyst in an Adult

Toyonaga

Matsuda

Mibu

et al. 2018

J Anus Rectum Colon

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Abstract:Anal canal duplication (ACD) is a rare congenital malformation, usually detected early in life. We report a case of a 67-year-old female with symptomatic ACD associated with a presacral cyst. Physical examination revealed an accessory opening located in the midline, posterior to the true anus. Imaging examinations, including fistulography, endoanal ultrasonography, and magnetic resonance imaging, revealed a blindending fistulous tract without connecting with the rectum and a presacral cyst posterior to the rectum. Complete surgical excision of the tract with cyst was performed through a posterior sagittal approach. Histologic examination revealed squamous epithelium lining and smooth muscle bundles, thereby confirming ACD. The postoperative course was uneventful, and the patient was doing well; no recurrence was observed 4 years after surgery. ACD can present for the first time in infants, children, and adults. Imaging examinations are useful for the diagnosis and preoperative assessment of ACD. Therefore, ACD should be considered in the differential diagnosis, even in adults, when a posterior perineal orifice is encountered, particularly in female patients. Once ACD is suspected, intense imaging inspection is recommended to visualize the ACD and associated anomalies, and surgical removal is warranted to prevent inflammatory complications or malignant changes.

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Section: Discussionmentioning

confidence: 99%

Section: Introductionmentioning

confidence: 99%

Section: Introductionmentioning

confidence: 99%

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Anal Canal Duplication Associated with Presacral Cyst in an Adult

Toyonaga

Matsuda

Mibu

et al. 2018

J Anus Rectum Colon

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“…2018;9(2):61-63 [1,2,6]. Neoplasia is the most feared complication, yet it was only described by Dukes and Galvin in 1956.…”

Section: Discussionmentioning

confidence: 99%

“…Diagnosis is usually made in the first year of life by caregivers [1]. In some cases the diagnosis is made at a later stage with the appearance of infectious complications [6]. The majority remains asymptomatic [1,4].…”

Section: Discussionmentioning

confidence: 99%

Anal Canal Duplication in a 40-Year-Old Adult

et al. 2018

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Anal canal duplication (ACD) is the rarest congenital malformation of the digestive tract and is associated with other congenital malformations. The clinical case reports a 40 years old woman who had two episodes of anal abscesses treated with surgical drainage within 1 year. In proctology consultation, the examination revealed a structure in the midline, posterior to the native anus. Pelvic magnetic resonance imaging and anal echoendoscopy confirmed the presence of a tubular structure posterior to the anal canal, compatible with duplication of the anal canal. The patient was proposed for surgical excision but refused. Seven years later, the patient had another anal abscess. She was again proposed for surgery and refused. Around 60 cases of ACD are currently described worldwide. The diagnosis is usually made at an early stage of life. Our patient was diagnosed at the age of 40 years, constituting one of the most elderly patient diagnosed with ACD.

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Anal canal duplication and triplication: a rare entity with different presentations

et al. 2017

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Anal canal duplication (ACD) is the rarest of gastrointestinal duplications. Few cases have been reported. Most cases present as an opening in the midline, posterior to the normal anus. The aim of our revision is to contribute with eight new cases, some of them with unusual presentations: five presented as the typical form, one with a perianal nodule, and two presented as two separate orifices (anal canal triplication). Complete excision was performed in all patients with no complications. ACD is the most distal and the least frequent digestive duplication. Its treatment should be surgical excision, to avoid complications such as abscess, fistulization, or malignization. Anal canal triplication has never been described before.

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Late Presentation of Anal Canal Duplication in Adults: A Series of Four Rare Cases

Cited by 41 publications

References 7 publications

Anal Canal Duplication Associated with Presacral Cyst in an Adult

Anal Canal Duplication Associated with Presacral Cyst in an Adult

Anal Canal Duplication in a 40-Year-Old Adult

Anal canal duplication and triplication: a rare entity with different presentations

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