Kaposiform Hemangioendothelioma of the Tongue in an Adult

White, Jeremy B.; Pullman, James; Wenig, Bruce M.; Smith, Richard V.

doi:10.1001/archoto.2009.104

Cited by 15 publications

(6 citation statements)

References 15 publications

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“…Only 1 case of khe of the tongue-White et al 5 -has been reported in the literature. However, the patient described by those authors was 21 years of age and had associated comorbidities of hypertension and systemic lupus erythematosus with chronic renal failure.…”

Section: Discussionmentioning

confidence: 99%

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Adult-Onset Kaposiform Hemangioendothelioma of the Tongue: Case Report and Review of the Literature

Vashi¹,

Abboud

Bier‐Laning

et al. 2016

Current Oncology

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We present here a very rare clinical case of a 38-year-old man with Kaposiform hemangioendothelioma (khe) of the tongue who presented to our institution with a growth under the left side of the tongue with no pain or discomfort. There were no enlarged lymph nodes and no significant neurologic findings. Diagnostic histopathology confirmed the lesion to be khe. The tumour was removed surgically, and the surgical specimen confirmed the diagnosis. Follow-up at 3 months shows no clinical evidence of recurrence.

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Section: Discussionmentioning

confidence: 99%

“…Only 1 adult case of khe in the tongue has been reported 5 . To the best of our knowledge, ours is the second adult case of khe in the tongue.…”

Section: Introductionmentioning

confidence: 99%

Adult-Onset Kaposiform Hemangioendothelioma of the Tongue: Case Report and Review of the Literature

Vashi¹,

Abboud

Bier‐Laning

et al. 2016

Current Oncology

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“…A major clinical concern is a differentiation from the more sinister Kaposi sarcoma (KS), which is suspected in the setting of an immunocompromised patient. Periodic acid Schiff (PAS) positivity and better histologic differentiation, in a background of HHV-8 positivity, points to a diagnosis of KS rather than KHE (12).…”

Section: Discussionmentioning

confidence: 99%

Kaposiform Hemangioendothelioma of the Sublingual Gland in an Adult: Resection is the Key.

Chowdhary

Sekar

Saxena

et al. 2021

Preprint

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Introduction: Kaposiform haemangioendotheliomas (KHE) are extremely rare, borderline malignant, locally aggressive vascular tumours. Although more commonly seen in childhood and adolescents, some very rare reports in adults do exist. KHE is usually found in the retroperitoneum, over the extremities and the soft tissues of the trunk, mediastinum and the head and neck regions. Prior published reports have shown a strong association with the Kasabach-Merritt phenomenon (KMP). We present a very rare case of KHE of the sublingual gland in an adult, which was not associated with KMP and was resected completely without any sequelae. Case report: A 42-year-old female presented with a painful swelling over the floor of the mouth on the right for a year. Clinical examination revealed a bi-digitally palpable, non-transilluminant lesion on the right side of the lingual frenulum. Radiological investigations suggested the possibility of a benign soft tissue tumour arising from the sublingual gland. The patient underwent an intraoral excision of the lesion. The biopsy revealed spindle-shaped tumour cells in fascicles, surrounded by vascular spaces, suggestive of a KHE. The patient was offered radiation therapy, which she declined and continued to be on follow-up for two years. She remains symptom-free to date.Conclusion: Excision of a KHE of the floor of the mouth proved to be sufficient, without the evidence of any residual lesion or progression of symptoms. To the best of our knowledge, our case represents the first reported case in the literature of a KHE arising from the salivary glands in an adult.

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“…KHE typically occurs during infancy and in the first decade of life. Although KHE may also develop in adults, only approximately 20 adult KHE patients have been reported (table 1) [1,2,3,4,5,6,7,8,9,10,11,12,13,14,15,16,17]; most of them were not associated with KMS [6]. KHE rarely originates from bone without accompanying cutaneous changes.…”

Section: Introductionmentioning

confidence: 99%

CyberKnife Treatment for Kaposiform Hemangioendothelioma of the Ilium in an Adult: Case Report and Review of the Literature

Wang¹,

Kong

Wu³

et al. 2014

Oncol Res Treat

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Background: Kaposiform hemangioendothelioma (KHE) is a rare vascular neoplasm that mainly affects infants. KHE rarely develops in adolescents and adults. These tumors tend to be locally invasive, but are not known to produce distant metastases. Numerous treatment modalities are available for KHE, but the optimal therapy is unknown. Case Report: A 51-year-old woman was diagnosed with KHE of the ilium in September 2005. The lesion recurred within 5 years of local excision, and was subsequently treated with CyberKnife. Within 1 month of CyberKnife therapy, pain intensity was significantly reduced and the patient's quality of life was significantly improved. Since January 2011, she has remained pain-free and has had no signs of recurrence or metastasis for more than 2 years following CyberKnife therapy. Conclusion: We report the first CyberKnife treatment of an adult with KHE of the bone without accompanying cutaneous changes and Kasabach-Merritt syndrome. CyberKnife treatment could be a useful temporizing measure for bone KHE.

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Kaposiform Hemangioendothelioma of the Tongue in an Adult

Cited by 15 publications

References 15 publications

Adult-Onset Kaposiform Hemangioendothelioma of the Tongue: Case Report and Review of the Literature

Adult-Onset Kaposiform Hemangioendothelioma of the Tongue: Case Report and Review of the Literature

Kaposiform Hemangioendothelioma of the Sublingual Gland in an Adult: Resection is the Key.

CyberKnife Treatment for Kaposiform Hemangioendothelioma of the Ilium in an Adult: Case Report and Review of the Literature

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