A 70-year-old man was admitted to our emergency department for sudden onset of abnormal involuntary movements involving his upper and lower left limbs. Hemichoreal movements were restricted to his left limbs, associated with rare episodes of hemiballism (video). There were no cranial nerve alterations, no sensory loss or limb weakness. The patient reported mild hypertension under treatment. There was no history of diabetes mellitus or epilepsy, no prior exposure to neuroleptics or recent change in therapy. He denied any similar previous episode or family history of movement disorders.Chest radiography, electrocardiography, and laboratory tests including glucose, glycated hemoglobin, coagulation parameters, and immunoglobulin electrophoresis were normal. Brain non-contrast CT scan on admission showed no signs of acute ischemia (Fig. 1a). A supra-aortic-trunk Doppler sonography revealed an irregular surface plaque, partly ulcerated, on the origin of the right internal carotid artery with stenosis of about 90 %, confirmed at CT angiography (Fig. 1b).