Facial asymmetry: a case report of localized linear scleroderma patient with muscular strain and spasm

Kim, Jae-Hyung; Lee, Suck-Chul; Kim, Chul-Hoon; Kim, Bok-Joo

doi:10.1186/s40902-015-0029-x

Cited by 8 publications

(4 citation statements)

References 16 publications

Supporting

Mentioning

Contrasting

Order By: Relevance

“…Of the currently available treatments, most experts prefer BTX-A injection. In uncomplicated HMS, some research has found electrophysiologically similar potentials to the facial nerve of hemifacial spasm ( 12 – 18 , 20 ). In recent years, an increasing number of experts concur with the neurovascular conflict theory and have attempted to apply simple microvascular decompression to the treatment of HMS, all of which have achieved a certain level of therapeutic effects ( 6 – 8 , 10 ).…”

Section: Discussionmentioning

confidence: 99%

Treatment of hemimasticatory spasm secondary to parry-romberg syndrome via partial resection of the trigeminal nerve motor branch under intraoperative neurophysiological monitoring: A case report and literature review

Xu¹,

Xu²,

Huang³

et al. 2023

Front. Surg.

View full text Add to dashboard Cite

Parry-Romberg syndrome (PRS) combined with hemimasticatory spasm (HMS) is a rare craniofacial disorder characterized by unilateral facial tissue atrophy with paroxysmal involuntary contractions of the jaw-closing muscles. Although a majority believe that this is a result of demyelination changes from the effect of the facial involvement of PRS on the trigeminal nerve motor branches, the mechanism of PRS is presently unclear. Moreover, the therapeutic effects of existing drugs that target PRS have not been satisfactory. For intolerable spasms of the masticatory muscles, botulinum toxin injection may temporarily relieve the symptoms of spasms. We report a case of HMS secondary to PRS that was treated via a partial resection of the trigeminal nerve motor branch under intraoperative neurophysiological monitoring.

show abstract

Section: Discussionmentioning

confidence: 99%

Treatment of hemimasticatory spasm secondary to parry-romberg syndrome via partial resection of the trigeminal nerve motor branch under intraoperative neurophysiological monitoring: A case report and literature review

Xu¹,

Xu²,

Huang³

et al. 2023

Front. Surg.

View full text Add to dashboard Cite

show abstract

“…Imaging and biopsy with immunohistochemical tests may be instrumental. The differential diagnosis for PRS includes other conditions within the scleroderma classification, such as en coup de sabre , as well as Rasmussen encephalitis, and other diseases characterized by facial asymmetry, such as hemifacial macrosomia and Goldenhar syndrome …”

Section: Discussionmentioning

confidence: 99%

New Ophthalmoplegia and Recurrent Ptosis After Ptosis Repair Surgery

Kostina

Lesser

2018

JAMA Ophthalmol

View full text Add to dashboard Cite

A man in his 60s with a history of surgery to repair right upper eyelid ptosis 1 year prior presented to a neuro-ophthalmology clinic with limited movement of the right eye of 1 year's duration and worsening recurrent ptosis of the same eye. Results of previous single-fiber electromyography and serologic testing for acetylcholine receptor-binding antibodies were negative for myasthenia gravis. His ocular history included amblyopia and nonarteritic ischemic optic neuropathy of the left eye. His medical history included obstructive sleep apnea, coronary artery disease, coronary artery bypass surgery, and prostate cancer, the last in remission for the past 4 years.Visual acuities were 20/30 OD and hand motions OS. The patient had an Adie pupil in his right eye and a relative afferent pupillary defect in the left eye. The right eye demonstrated total ophthalmoplegia, and no deficit was found in the left (Figure 1). Exophthalmometer measurements demonstrated enophthalmos of the right eye associated with facial asymmetry. Margin reflex distance was 0 mm in the right eye and 4 mm in the left. In-office ice and sleep testing did not improve the ptosis or ophthalmoplegia in the right eye. The remainder of his examination was remarkable for punctate epithelial erosions of the right eye and optic atrophy of the left.

show abstract

“…Therefore, clinicians should consider each case's individual disease activity when choosing the operation period [ 2 ]. Furthermore, when a coexisting bone deformity is suspected, image work-up (e.g., three-dimensional-computed tomography) and bone surgery should be considered [ 2 17 ].…”

Section: Discussionmentioning

confidence: 99%

Surgical Management of Localized Scleroderma

Lee

Lim

Lee

et al. 2017

Arch Craniofac Surg

View full text Add to dashboard Cite

BackgroundLocalized scleroderma is characterized by a thickening of the skin from excessive collagen deposits. It is not a fatal disease, but quality of life can be adversely affected due to changes in skin appearance, joint contractures, and, rarely, serious deformities of the face and extremities. We present six cases of localized scleroderma in face from our surgical practice.MethodsWe reviewed six localized scleroderma cases that were initially treated with medication and then received follow-up surgery between April 2003 and February 2015. Six patients had facial lesions. These cases presented with linear dermal sclerosis on the forehead, oval subcutaneous and dermal depression in the cheek.ResultsEn coup de sabre (n=4), and oval-shaped lesion of the face (n=2) were successfully treated. Surgical methods included resection with or without Z-plasty (n=3), fat graft (n=1), dermofat graft (n=1), and adipofascial free flap (n=1). Deformities of the affected parts were surgically corrected without reoccurrence.ConclusionWe retrospectively reviewed six cases of localized scleroderma that were successfully treated with surgery. And we propose an algorithm for selecting the best surgical approach for individual localized scleroderma cases. Although our cases were limited in number and long-term follow-up will be necessary, we suggest that surgical management should be considered as an option for treating scleroderma patients.

show abstract

Facial asymmetry: a case report of localized linear scleroderma patient with muscular strain and spasm

Cited by 8 publications

References 16 publications

Treatment of hemimasticatory spasm secondary to parry-romberg syndrome via partial resection of the trigeminal nerve motor branch under intraoperative neurophysiological monitoring: A case report and literature review

Treatment of hemimasticatory spasm secondary to parry-romberg syndrome via partial resection of the trigeminal nerve motor branch under intraoperative neurophysiological monitoring: A case report and literature review

New Ophthalmoplegia and Recurrent Ptosis After Ptosis Repair Surgery

Surgical Management of Localized Scleroderma

Contact Info

Product

Resources

About