Extralobar pulmonary sequestration presenting as hemothorax

Tetsuka, Kenji; Endo, Shunsuke; Kanai, Yoshihiko; Yamamoto, Shinichi

doi:10.1510/icvts.2009.209254

Cited by 13 publications

(14 citation statements)

References 8 publications

Supporting

Mentioning

Contrasting

Order By: Relevance

“…It was first described in 1861 by Rokitansky and Rektorik. 2 There is no consensus regarding the etiology of PS, but there are two possible hypotheses: formation and caudal migration of a supernumerary pulmonary bud that accompanies the esophagus and primary pulmonary vascular deficiency, which would explain the persistence of systemic collateral circulation. 1,6 PS accounts for 0.15% to 6% of all congenital pulmonary malfunctions.These lesions are divided into two types on the basis of their pleural coverings.…”

Section: Discussionmentioning

confidence: 99%

“…Although PS is mostly asymptomatic in the neonatal period, severe respiratory distress syndrome, congestive heart failure, hydrothorax, pneumonia may happen in infancy. [1][2][3] In our case, the clinical findings were pulmonary hemorrhage and respiratory failure developed shortly after birth.…”

Section: Discussionmentioning

confidence: 99%

“…ELPS can be located at mediastinum or subphrenic space. 1,2 ELPS is mostly asymptomatic. Symptomatic PS is usually an intralobar type presenting as infection, hemoptysis and hemothorax caused by communication to the airway.…”

Section: Introductionmentioning

confidence: 99%

See 2 more Smart Citations

Extralobar pulmonary sequestration as a cause of recurrent pulmonary hemorrhage in a neonate

et al. 2016

View full text Add to dashboard Cite

Pulmonary sequestration is acystic or solid congenital lung malformation comprised of non functional lung tissue that does not communicate with the normal tracheobronchial tree and has a systemic arterial blood supply. There aretwo forms of sequestration: intralobar and extralobar. Its treatment is surgical resection. Here we presented a case of premature neonate with extralobar pulmonary sequestration who had respiratory failure and recurrent pulmonary hemorrhage. Following surgery, the patient showed significant clinical improvement.

show abstract

Section: Discussionmentioning

confidence: 99%

Section: Discussionmentioning

confidence: 99%

See 1 more Smart Citation

Extralobar pulmonary sequestration as a cause of recurrent pulmonary hemorrhage in a neonate

et al. 2016

View full text Add to dashboard Cite

show abstract

“…In one previous case, resection of the sequestrum required concomitant partial resection of the diaphragm due to dense adhesion 14 days after the clinical presentation [7]. Dense adhesion can complicate dissection from the surrounding organs, therefore early surgical resection is recommended.…”

Section: Discussionmentioning

confidence: 99%

Extralobar pulmonary sequestration manifesting as hemorrhagic infarction in a five-year-old male

Higashidate

Iinuma

Kanazawa

et al. 2015

Journal of Pediatric Surgery Case Reports

View full text Add to dashboard Cite

a b s t r a c tExtralobar pulmonary sequestration (EPS) is frequently asymptomatic and detected incidentally. We herein report a pediatric case of EPS that manifested as hemorrhagic infarction. A five-year-old male with previously normal X-ray films was referred to our hospital due to acute onset of right flank pain and a non-productive cough. The initial diagnosis was infection of an EPS; however, the symptoms persisted despite the administration of antibiotics. A CT-angiogram revealed interruption of the blood flow to the sequestrum, and a definitive diagnosis as hemorrhagic infarction of a pulmonary sequestration was made. During surgery, an aberrant artery was revealed to derive from the intercostal artery and the sequestrum was resected safely. In cases of infarction of EPS, early surgical resection should be considered, because progressed adhesion can complicate dissection from surrounding organs and the detection of the feeding vessels. Ó 2015 The Authors. Published by Elsevier Inc. This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).A pulmonary sequestration is defined as a mass of abnormal lung tissue which has no bronchial communication with the normal tracheobronchial tree. Pulmonary sequestrations are divided into two groups; extralobar and intralobar sequestrations, based on whether they have their own visceral pleura. Extralobar pulmonary sequestration (EPS) is usually asymptomatic and detected incidentally during examinations for other clinical conditions [1]. We herein report a case of symptomatic EPS with massive bloody pleural effusion, and the initial symptom was a sudden onset of right flank pain. The pathological findings were compatible with hemorrhagic infarction of an EPS. We also review other previously reported cases of this condition. Case reportA five-year-old male was referred to our hospital due to a sudden onset of right flank pain and a non-productive cough. The patient had a past history of acute bronchitis when he was twoyears-old and had undergone adenoidectomy when he was fouryears-old. The patient received X-ray examinations each time, in which pulmonary sequestration was not found. Radiologic abnormalities were not identified even though our radiologists reviewed these X-ray films. At this presentation, the patient's temperature was 38.4 C, his pulse was 140 bpm and his respirations were 60/ min. The breath sounds were diminished over the right lower lobe. He had remarkable right flank pain, but there were no signs of peritoneal irritation or ascitic fluid. A peripheral blood examination showed elevation of the white blood cell count to 13,000 and a serum C-reactive protein concentration of 8.03 mg/dl. An X-ray film of the chest showed opacification of the right hemithorax. A contrast-enhanced computed tomography (CECT) scan revealed the presence of a solitary triangle mass without enhancement, adjacent to the posterior portion of the right lower lobe (Fig. 1). In addition, massive pleural effusion was demonstrated,...

show abstract

“…1) Because the symptoms are not typical, pulmonary sequestration is often misdiagnosed as bronchiectasis, congenital emphysema, hemothorax, and even lung cancer. 2,3) Routine chest X-ray and computed tomography (CT) scan have difficultly showing abnormal blood vessels clearly. Threedimensional computed tomographic angiography (3D CTA) can depict an aberrant blood supply from systemic circulation to the consolidation accurately and intuitively, thereby greatly improving the diagnosis rate preoperatively and reducing the surgical risk.…”

Section: Introductionmentioning

confidence: 99%

Extralobar Pulmonary Sequestration in a 55-Year-Old Man

Han

Shi

Gong

et al. 2014

ATCS

View full text Add to dashboard Cite

Pulmonary sequestration is a rare congenital lung malformation that more commonly occurs in the left lung, mainly near the lower mediastinum. It is rarely observed in patients with extralobar sequestration in adulthood. We report the case of a 55-year-old man with recurrent fever and cough lasting for about 1 month, who was admitted to our hospital. His past history was unremarkable. The final diagnosis of extralobar sequestration was dependent on three-dimensional computed tomography angiography (3D CTA), which showed an abnormal blood supply vessel to the consolidation from the aortic arch. The patient underwent a left pulmonary sequestration resection, and the pathological examination also verified the diagnosis postoperatively. 3D CTA images can provide an aberrant vessel anatomy map for the surgeon and play a decisive role in the detection of pulmonary sequestration.

show abstract

Extralobar pulmonary sequestration presenting as hemothorax

Cited by 13 publications

References 8 publications

Extralobar pulmonary sequestration as a cause of recurrent pulmonary hemorrhage in a neonate

Extralobar pulmonary sequestration as a cause of recurrent pulmonary hemorrhage in a neonate

Extralobar pulmonary sequestration manifesting as hemorrhagic infarction in a five-year-old male

Extralobar Pulmonary Sequestration in a 55-Year-Old Man

Contact Info

Product

Resources

About