Cutaneous ciliated cyst on the anterior neck in young women: A case report

Kim, Yon Hee; Lee, Jihyoun

doi:10.12998/wjcc.v8.i19.4481

Cited by 4 publications

(3 citation statements)

References 34 publications

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“…Consequently, during menarche hormonal stimulation plays a role in the growth of those cystic formations (2)(3)(4)(5). A second theory, concerning the etiological background of this entity, supports the cilia metaplasia of the eccrine glands.…”

Section: Discussionmentioning

confidence: 95%

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A Remarkably Rare Position of a Cutaneous Ciliated Cyst in a 16 Month-old Female

Anastasakis

Gkalonaki

Doitsidis

et al. 2023

ama

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Objective. The aim of the work was to show a Cutaneous Ciliated Cyst (CCC) in an unusual location in a 16-month-old girl.Case Report. We present the case of a 16-month otherwise healthy girl presented to our hospital, with a report of a palpable mass in the left suprascapular region. Physical examination revealed a soft-textured, fluctuating, mobile and painless entity, with no further indications of local inflammation. The mass was totally excised, under general anesthesia, for both diagnostic and therapeutic purposes. According to the histopathological findings, the cystic lesion was covered by a pseudostratified ciliary epithelium, resembling the epithelium of a normal fallopian tube, surrounded by a smooth muscle layer. Immunohistochemical studies identified the cyst epithelium as having cytokeratin (CKAE1/AE3) expression, despite the negative immunostaining findings on Estrogen and Progesterone Receptors.Conclusion. Our case report concerns a CCC in an unusual position, in the suprascapular area. After a thorough review of the international literature, we concluded that this is the second published case regarding this specific location. To our knowledge our patient is the youngest ever diagnosed with CCC.

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Section: Discussionmentioning

confidence: 95%

“…In the recent review by Yon Hee Kim et al 31 patients were recorded, including both sexes, using the PubMed search. The youngest was 7 years old ( 4 ). This statement demonstrates that our 16-month girl is the youngest to be diagnosed with CCC described in the literature.…”

Section: Discussionmentioning

confidence: 99%

A Remarkably Rare Position of a Cutaneous Ciliated Cyst in a 16 Month-old Female

Anastasakis

Gkalonaki

Doitsidis

et al. 2023

ama

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“…Cutaneous ciliated cysts are rare benign lesions commonly occur in the perineum and lower extremities of women in their reproductive years. 16,17 As the name implied, the cyst lining is composed of cuboidal and columnar ciliated epithelium with some cases displaying a pseudostratified architecture. Because the lining epithelial cells are commonly positive for ER, PR, and PAX-8, 16,18 it is believed to derive from Müllerian heterotopic tissue.…”

Section: The Most Unusual Type Of Syringometaplasia In This Casementioning

confidence: 99%

Ciliated and Mucinous Adenomatous Syringometaplasia: The Missing Link of the “Ciliated Eccrine Metaplasia” Theory in the Histogenesis of Cutaneous Eccrine Ciliated Cyst?

Tran¹

2021

The American Journal of Dermatopathology

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A variety of metaplastic changes has been reported in eccrine ducts and glands with squamous and mucinous syringometaplasia representing the most common histopathologic patterns. In the current case, a previously unreported variant of syringometaplasia was described in a female newborn with a 2-cm occipital cutaneous defect consistent with cutis aplasia. Over a more than 1-year period of local treatment, an enlarging plaque associated with local alopecia developed at the site of the original ulcerated area. A local excision demonstrated a superficial hypertrophic scar associated with a complete loss of hair follicles. In addition, there was a proliferation of eccrine glands and ducts lined by cuboidal epithelial cells arranged in a linear distribution beneath the scar area. Focal anastomosing of the proliferative ducts was identified. In few dilated ducts, the epithelial lining was composed of an inner layer of columnar cells with wellformed apical cilia and intracytoplasmic mucin and an outer layer of myoepithelial cells. The mucinous and ciliated cells were positive for epithelial membranous antigen and carcinoembryonic antigen, but negative for estrogen receptors, progesterone receptors, and thyroid transcription factor-1. Because this variant of eccrine metaplasia has not hitherto been reported in the literature, the term ciliated and mucinous adenomatous syringometaplasia was proposed for this unusual histologic finding. Mucinous and ciliated adenomatous syringometaplasia not only expands the spectrum of metaplastic changes in sweat gland units, but also might represent the missing link in the histogenesis of a subset of cutaneous ciliated cysts.

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A rare case of a cutaneous ciliated cyst of Mullerian origin found in the lower extremity: A case report

Hill¹,

Stone²,

Weiner³

et al. 2023

Foot & Ankle Surgery: Techniques, Reports & Cases

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Cutaneous ciliated cyst on the anterior neck in young women: A case report

Cited by 4 publications

References 34 publications

A Remarkably Rare Position of a Cutaneous Ciliated Cyst in a 16 Month-old Female

A Remarkably Rare Position of a Cutaneous Ciliated Cyst in a 16 Month-old Female

Ciliated and Mucinous Adenomatous Syringometaplasia: The Missing Link of the “Ciliated Eccrine Metaplasia” Theory in the Histogenesis of Cutaneous Eccrine Ciliated Cyst?

A rare case of a cutaneous ciliated cyst of Mullerian origin found in the lower extremity: A case report

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