The ectopic thyroid gland is a rare congenital disorder. It occurs in most cases at the level of the cervical midline and rarely in lateral submandibular topography. We present the case of a 44-year-old woman who consulted for a painful, progressively growing right submandibular tumor in which a diagnosis of ectopic multinodular goiter was made and surgical treatment by resection of the thyroid tissue was decided. She always presented normal thyroid function and the reason for surgery was the neck deformity that bothered the patient and the pain. In the postoperative period, she presented TSH of 40 and levothyroxine was started. We present this case because cases of submandibular ectopic multinodular goiter as the only functioning tissue are rare.