A case of IgG4-related disease with initial symptoms in the labial salivary gland

Hiraoka, Shin-ichiro; Matsukawa, M.; Noda, Yuri; Sasai, Tadashi; Kishino, Mitsunobu; Kogo, Mikihiko

doi:10.1016/j.ajoms.2016.05.004

Cited by 1 publication

(2 citation statements)

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“…Other oral sites were described only in few papers: the alveolar mucosa and the floor‐of‐the‐mouth were cited only by one study discussing three cases of soft tissue masses resembling plasma cell granuloma 43 . Similarly, only two cases were associated with the lower lip, one presenting as a single, elliptical, movable mass, 44 and the other one as a bilateral swelling 45…”

Section: Scoping Review: Resultsmentioning

confidence: 99%

“…42 Other oral sites were described only in few papers: the alveolar mucosa and the floor-of-the-mouth were cited only by one study discussing three cases of soft tissue masses resembling plasma cell granuloma. 43 Similarly, only two cases were associated with the lower lip, one presenting as a single, elliptical, movable mass, 44 and the other one as a bilateral swelling. 45 Interestingly, two cases exhibited diffuse aphthouslike sores in the mouth, suggesting a clinical diagnosis of Behçet's disease, but in these cases the primary site of IgG4-RD was the larynx.…”

Section: Clinical Presentationmentioning

confidence: 99%

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The “great imitator”: IgG4‐related disease of the oral cavity. Two case reports and scoping review

Azzi,

Magnoli,

Krepysheva

et al. 2024

Head & Neck

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This study aimed to review the lesser‐known intraoral manifestations of immunoglobulin G4‐related disease (IgG4‐RD). In this paper we report an unprecedented case of oral IgG4‐RD mimicking angiolymphoid hyperplasia with eosinophilia (ALHE), and another case presenting as plasma cell gingivitis. We then performed a scoping review of published cases of IgG4‐RD involving the oral cavity. The following data were collected for each case: age, sex, intraoral site(s) involved, clinical appearance, imaging features, serum IgG4 values, histopathology, treatment, and follow‐up duration. Fifty‐one cases of oral IgG4‐RD were published in literature. The hard palate and jaw bones were the two main locations reported, while the histological identification of a IgG4/IgG plasma cells ratio ≥40% was fundamental for diagnosis. Conversely, the pathological features of storiform fibrosis and obliterative phlebitis were not common. Future reports regarding oral IgG4‐RD should report clear adherence to the recognized international diagnostic criteria of the disease.

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Section: Scoping Review: Resultsmentioning

confidence: 99%