A case of linear atrophoderma of Moulin

Zhang, Liwen; Ma, Mengsha; Chen, Tao; Fu, Lianshe

doi:10.1016/j.abd.2019.03.005

Cited by 2 publications

(3 citation statements)

References 4 publications

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“…trunk and extremities 3,5 . Its course is asymptomatic with an absence of systemic involvement or progression 6 .…”

Section: Discussionmentioning

confidence: 99%

“…Regarding treatment, various drugs have been used, ranging from topical steroids, platelet-rich plasma, PUVA therapy (psoralen (P) and long-wavelength ultraviolet radiation (UVA)), oral potassium, and high-dose penicillin, without optimal results 1,6 . A case treated with methotrexate at a dose of 20 mg per week was reported, where improvement in skin color and texture was clinically demonstrated after 6 months of treatment 1 .…”

Section: Discussionmentioning

confidence: 99%

“…Differential diagnoses of LAM include conditions affecting Blaschko's lines such as linear and whorled nevoid hypermelanosis, incontinentia pigmenti, lichen striatus, epidermal nevi, and atrophoderma of Pasini and Pierini (APP) 5,6,37 . A review of the transcendent conditions to establish the diagnosis of LAM is made.…”

Section: Discussionmentioning

confidence: 99%

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Hyperpigmented lesions with acquired atrophy following Blaschko lines in a patient with diagnosed with localized scleroderma

Marín-Hernández¹,

Suárez-Frías²,

Reyes³

2021

BMHIM

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Background: Linear atrophoderma of Moulin (LAM) is a dermatosis that affects children and adolescents characterized by hyperpigmented and atrophic linear lesions following Blaschko lines. So far, less than 50 cases have been published. Therefore, it is a rare entity with unknown etiology and a chronic and self-limited course. Histologically, it is described as hyperpigmentation of the basal layer without the involvement of the dermis and subcutaneous tissue. No specific treatment exists currently. Localized scleroderma is a chronic and progressive autoimmune connective tissue disorder that affects the skin and adjacent tissues, characterized by abnormal collagen deposition and alteration in elastic fibers, blood vessels, and annexes. No reports have been published on the coexistence of localized scleroderma and LAM. Case report: We describe the case of an 11-year-old male with a clinical diagnosis of linear scleroderma since 5 years of age. Four years later, the patient developed atrophic and hyperpigmented lesions following Blaschko lines in the posterior trunk. A biopsy of both dermatoses was performed: the trunk showed epidermis with hyperpigmentation of the basal layer, and within the dermis, no alteration in the collagen bundles; the forearm biopsy corroborated scleroderma. Based on the clinical-pathological correlation, LAM coinciding with localized linear scleroderma was diagnosed. Conclusions: LAM is an infrequent entity by itself. Moreover, its coexistence with sclerodermiform syndrome has not been reported in the indexed literature.

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“…trunk and extremities 3,5 . Its course is asymptomatic with an absence of systemic involvement or progression 6 .…”

Section: Discussionmentioning

confidence: 99%

Section: Discussionmentioning

confidence: 99%

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Hyperpigmented lesions with acquired atrophy following Blaschko lines in a patient with diagnosed with localized scleroderma

Marín-Hernández¹,

Suárez-Frías²,

Reyes³

2021

BMHIM

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Linear atrophoderma of Moulin: A rare case report and review of the literature

Hussein Al‐janabi,

Diab,

Aljammal

et al. 2024

Skin Health and Disease

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Linear atrophoderma of Moulin (LAM) is an uncommon dermatological disease characterised by linear, depressed plaques typically following Blaschko's lines. LAM generally occurs in adolescence or early adulthood and is more commonly observed in females. The aetiology of LAM is still unclear. We report a rare case of LAM in an 18‐year‐old female presenting with an atypical Blaschkoid distribution (multiple band‐like pattern) on her right trunk. A clinical examination and histopathological analysis were performed to make the diagnosis. Partial improvement was obtained with calcipotriol and colchicine. LAM is a rare condition; we were only able to identify 23 case reports in the published literature. The findings of this report contribute to the limited literature on LAM, highlighting the clinical variability of LAM and suggesting potential novel variants beyond the classic presentation, emphasising the importance of recognising diverse manifestations for accurate diagnosis and management. Early recognition of LAM is crucial for appropriate treatment and improved patient outcomes. Further research is needed to elucidate LAM's aetiology and underlying mechanisms to facilitate the development of more targeted therapeutic strategies.

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A case of linear atrophoderma of Moulin

Cited by 2 publications

References 4 publications

Hyperpigmented lesions with acquired atrophy following Blaschko lines in a patient with diagnosed with localized scleroderma

Hyperpigmented lesions with acquired atrophy following Blaschko lines in a patient with diagnosed with localized scleroderma

Linear atrophoderma of Moulin: A rare case report and review of the literature

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